Idiopatic Infantile Arterial Calcification: Echocardiography Diagnosis and Successful Treatment

Hasan Onal; Neval Topal; Melek Yıldız; Banu Aydın; Aygün Dindar

Case Report

Idiopatic Infantile Arterial Calcification: Echocardiography Diagnosis and Successful Treatment

Year 2019, Volume: 2 Issue: 1, 27 - 28, 15.10.2019

Hasan Onal Neval Topal Melek Yıldız Banu Aydın Aygün Dindar

Abstract

Idiopathic
infantile arterial calcification is
rare disease characterized by medial calcification and intimal proliferation of
large and medium size arteries (1).

Prenatal prezantation is usually with nonimmune
hidrops and polyhydamnios (2). Although the clinical characteristics in
neonatal period is variable, respiratory distress with cardiac failure is the
most common finding. Hypertension due to poor compliance caused by diffuse
arterial calcification of the vessels is present in most patients.

Clinical experience in treating this rare disorder is
limited. We present a neonatal case with Idiopathic infantile
arterial calcification
who was treated with etidronate disodium, successfully.

Keywords

Arterial Calcification

References

1. Juul S, Ledbetter, Wight TN, Woodrum D. New insight into idiopathic infantile arterial calcinosis. Am J Dis Child. 144(2):229-33.
2. Nagar AM, Hanchate V, Tandon A, Thakkar H, Chaubal NG. Antenatal detection of idiopathic arterial calcification with hidrops fetalis. J Ultrasound Med 2003; 22(6): 653-9.
3. Bryant JH, White WA. A case of calcification of the arteries and obliterative endarteritis associated with hydronephrosis in child aged 6 months. Guys Hosp Rep 1901; 55: 17-28.
4. Samon LM, Ash KM, Murdison KA. Aorto-pulmonary calcification: an unusual manifestation of idiopathic calcification of infancy evident antenatally. Obstet Gynecol 1995; 85: 863-5.
5. Vera J, Lucaya J, Garcia Conesa JA, Aso C, Balaguer A. Idiopathic infantile arterial calcification: unusual features. Pediatr Radiol 1990; 20(8): 585-7.
6. Ciana G, Colonna F, Forleo V, Brizzi F, Benettoni A, de Vonderweid U. Idiopathic arterial calcification of infancy: effectiveness of prostaglandin infusion for treatment of secondary hypertension refractory to conventional therapy: case report. Pediatr Cardiol 1997; 18(1): 67-71.
7. Sholler GF, Yu JS, Bale PM, Hawker RE, Celermajer JM, Kozlowski K.. Generalized arterial calcification of infancy: three case reports, including spontaneous regression J Pediatr 1984; 105(2): 257-60.
8. von Bickel E, Janssen W. Arteriopathic calcifications infantum. Arch Kinderheilk. Unde 1963; 169: 274-85.
9. Meradji M, de Villenueve VH, Huber J, de Bruijn WC, Pearse RG. Idiopathic infantile arterial calcification in siblings: radiologic diagnosis and successful treatment. J Pedaitr 1978; 92: 401-5.
10. Stuart G, Wren C, Bain H. Idiopathic infantile arterial calcification in two siblings: failure of treatment with diphosphonate. Br Heart J 1990; 64(2): 156-9.

Year 2019, Volume: 2 Issue: 1, 27 - 28, 15.10.2019

Hasan Onal Neval Topal Melek Yıldız Banu Aydın Aygün Dindar

Abstract

References

1. Juul S, Ledbetter, Wight TN, Woodrum D. New insight into idiopathic infantile arterial calcinosis. Am J Dis Child. 144(2):229-33.
2. Nagar AM, Hanchate V, Tandon A, Thakkar H, Chaubal NG. Antenatal detection of idiopathic arterial calcification with hidrops fetalis. J Ultrasound Med 2003; 22(6): 653-9.
3. Bryant JH, White WA. A case of calcification of the arteries and obliterative endarteritis associated with hydronephrosis in child aged 6 months. Guys Hosp Rep 1901; 55: 17-28.
4. Samon LM, Ash KM, Murdison KA. Aorto-pulmonary calcification: an unusual manifestation of idiopathic calcification of infancy evident antenatally. Obstet Gynecol 1995; 85: 863-5.
5. Vera J, Lucaya J, Garcia Conesa JA, Aso C, Balaguer A. Idiopathic infantile arterial calcification: unusual features. Pediatr Radiol 1990; 20(8): 585-7.
6. Ciana G, Colonna F, Forleo V, Brizzi F, Benettoni A, de Vonderweid U. Idiopathic arterial calcification of infancy: effectiveness of prostaglandin infusion for treatment of secondary hypertension refractory to conventional therapy: case report. Pediatr Cardiol 1997; 18(1): 67-71.
7. Sholler GF, Yu JS, Bale PM, Hawker RE, Celermajer JM, Kozlowski K.. Generalized arterial calcification of infancy: three case reports, including spontaneous regression J Pediatr 1984; 105(2): 257-60.
8. von Bickel E, Janssen W. Arteriopathic calcifications infantum. Arch Kinderheilk. Unde 1963; 169: 274-85.
9. Meradji M, de Villenueve VH, Huber J, de Bruijn WC, Pearse RG. Idiopathic infantile arterial calcification in siblings: radiologic diagnosis and successful treatment. J Pedaitr 1978; 92: 401-5.
10. Stuart G, Wren C, Bain H. Idiopathic infantile arterial calcification in two siblings: failure of treatment with diphosphonate. Br Heart J 1990; 64(2): 156-9.

There are 10 citations in total.

Details

Primary Language	English
Subjects	Clinical Sciences
Journal Section	Articles
Authors	Hasan Onal 0000-0001-9676-7086 Neval Topal This is me Melek Yıldız This is me Banu Aydın This is me Aygün Dindar This is me
Publication Date	October 15, 2019
Submission Date	November 12, 2018
Published in Issue	Year 2019 Volume: 2 Issue: 1

Cite

Vancouver	Onal H, Topal N, Yıldız M, Aydın B, Dindar A. Idiopatic Infantile Arterial Calcification: Echocardiography Diagnosis and Successful Treatment. MRR. 2019;2(1):27-8.